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telomerase

Definition: Telomerase is a multimeric ribonucleoprotein complex consisting of at least a functional RNA (hTR) that contains the template region complementary to the telomeric sequence and a reverse transcriptase protein component (hTERT) that catalyzes the addition of telomeric repeats to the ends of chromosomes.

hTR is expressed in all tissues but hTERT is only highly expressed in specific germ line cells, proliferative stem cells of renewal tissues, and immortal cancer cells.

Functions

Telomeres are repetitive, non-coding DNA [TTAGGG] elements at the ends of chromosomes. In most human somatic cells, telomeres shorten with each cell division due to incomplete lagging DNA strand synthesis and oxidative damage.

Even cells that express telomerase (e.g. peripheral blood mononuclear cells and other stem-like cells) undergo telomere shortening with age.

Telomere lengths are affected by their starting set points, the cellular activity of telomerase, the cell’s history of cell division and environmental effects. Overexpression of the catalytic subunit of human telomerase (hTERT) induces telomerase activity and telomere elongation.

Chromosome stability requires a dynamic balance of DNA loss and gain in each terminal tract of telomeric repeats. Repeat addition by a specialized reverse transcriptase, telomerase, has an important role in maintaining this equilibrium.

Pathology of telomerases (Telomerase disease)

- cancer

- X-linked, autosomal dominant forms of congenital dyskeratosis

  • The X-linked form is due to mutations in the DKC1 gene at Xq28. The encoded protein, dyskerin, is a component of both small nucleolar ribonuclear protein particles and the telomerase complex. Mutations in DKC1 mainly lead to amino acid substitutions.
  • The autosomal dominant form of the disease is due to mutations in hTR, the RNA component of telomerase, making it likely that the disease is due to defective telomerase activity. Mutations in hTR are predicted to either disrupt secondary structure or alter the template region.

recessive forms : no genes known (2003)

References

- Collins K. The biogenesis and regulation of telomerase holoenzymes. Nat Rev Mol Cell Biol. 2006 Jul;7(7):484-94. PMID: #16829980#

- Boukamp P. Skin aging: a role for telomerase and telomere dynamics? Curr Mol Med. 2005 Mar;5(2):171-7. PMID: #15974870#

- Hahn WC. Telomere and telomerase dynamics in human cells. Curr Mol Med. 2005 Mar;5(2):227-31. PMID: #15974877#

- Opitz OG. Telomeres, telomerase and malignant transformation. Curr Mol Med. 2005 Mar;5(2):219-26. PMID: #15974876#

- Greenberg RA. Telomeres, crisis and cancer. Curr Mol Med. 2005 Mar;5(2):213-8. PMID: #15974875#

- Harley CB. Telomerase therapeutics for degenerative diseases. Curr Mol Med. 2005 Mar;5(2):205-11. PMID: #15974874#

- Wirth T, Kuhnel F, Kubicka S. Telomerase-dependent gene therapy. Curr Mol Med. 2005 Mar;5(2):243-51. PMID: #15974879#

- Chung HK, Cheong C, Song J, Lee HW. Extratelomeric functions of telomerase. Curr Mol Med. 2005 Mar;5(2):233-41. PMID: #15974878#

- Blasco MA, Hahn WC. Evolving views of telomerase and cancer. Trends Cell Biol. 2003 Jun;13(6):289-94. PMID: #12791294#

- Blasco MA. Telomerase beyond telomeres. Nat Rev Cancer. 2002 Aug ;2(8):627-33. PMID : #12154355#

- Shay JW, Zou Y, Hiyama E, Wright WE. Telomerase and cancer. Hum Mol Genet. 2001 Apr;10(7):677-85. PMID: #11257099#

- Ostler EL, Wallis CV, Aboalchamat B, Faragher RG. Telomerase and the cellular lifespan: implications of the aging process. J Pediatr Endocrinol Metab. 2000;13 Suppl 6:1467-76. PMID: #11202223#

- Greider CW. Telomerase activation. One step on the road to cancer? Trends Genet. 1999 Mar;15(3):109-12. PMID: #10203808#

- Kipling D. Mammalian telomerase: catalytic subunit and knockout mice. Hum Mol Genet. 1997 Nov;6(12):1999-2004. PMID: #9328462#