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Bart-Pumphrey syndrome

Bart-Pumphrey syndrome (BPS) is an autosomal dominant disorder characterized by sensorineural hearing loss, palmoplantar keratoderma, knuckle pads, and leukonychia, which show considerable phenotypic variability.

Nosological overlaps

- Vohwinkel syndrome
- Keratitis-Ichthyosis-Deafness syndrome

Etiology

- dominant mutations in the GJB2 gene encoding the gap junction protein connexin-26

References

- Richard G, Brown N, Ishida-Yamamoto A, Krol A. Expanding the phenotypic spectrum of Cx26 disorders: Bart-Pumphrey syndrome is caused by a novel missense mutation in GJB2. J Invest Dermatol. 2004 Nov;123(5):856-63. PMID: 15482471